Multiexon deletions account for 15% of congenital myasthenic syndromes with RAPSN mutations after negative DNA sequencing.

نویسندگان

  • Karen Gaudon
  • Isabelle Pénisson-Besnier
  • Brigitte Chabrol
  • Françoise Bouhour
  • Laurence Demay
  • Asma Ben Ammar
  • Stéphanie Bauché
  • Christophe Vial
  • Guillaume Nicolas
  • Bruno Eymard
  • Daniel Hantaï
  • Pascale Richard
چکیده

Congenital myasthenic syndromes (CMS) are a heterogeneous group of genetic disorders that give rise to a defect in neuromuscular transmission. We described here three patients with a characteristic phenotype of recessive CMS and presenting mutation in the gene encoding rapsyn (RAPSN). Familial analysis showed that one allelic mutation failed to be detected by direct sequencing. An allelic quantification on patient's DNA identified three novel multi-exon deletions of RAPSN. These three genomic rearrangements in RAPSN represent 15% of our CMS patients with RAPSN mutations and we emphasize that single-nucleotide polymorphism markers and a gene dosage method should be performed in addition to DNA direct sequencing analysis particularly when there is a genetic counselling issue.

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عنوان ژورنال:
  • Journal of medical genetics

دوره 47 12  شماره 

صفحات  -

تاریخ انتشار 2010